Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001922461 | SCV002171053 | pathogenic | Cystic fibrosis | 2021-08-11 | criteria provided, single submitter | clinical testing | This variant has not been reported in the literature in individuals affected with CFTR-related conditions. For these reasons, this variant has been classified as Pathogenic. This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Gln781*) in the CFTR gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in CFTR are known to be pathogenic (PMID: 1695717, 7691345, 9725922). |
Institute of Human Genetics, |
RCV001922461 | SCV002573822 | pathogenic | Cystic fibrosis | 2022-09-05 | criteria provided, single submitter | curation | This variant was identified in 3 unrelated patients with a clinically confirmed diagnosis of cystic fibrosis. The variant was classified in the context of a project re-classifying variants in the German Cystic Fibrosis Registry (Muko.e.V.). Link: https://www.muko.info/angebote/qualitaetsmanagement/register/cf-einrichtungen/mukoweb. Criteria applied: PVS1, PM2_SUP, PM3, PP4 |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV001922461 | SCV004037689 | pathogenic | Cystic fibrosis | 2023-08-29 | criteria provided, single submitter | clinical testing | Variant summary: CFTR c.2341C>T (p.Gln781X) results in a premature termination codon, predicted to cause a truncation of the encoded protein or absence of the protein due to nonsense mediated decay, which are commonly known mechanisms for disease. The variant was absent in 186868 control chromosomes. c.2341C>T has been reported in the literature in individuals affected with Cystic Fibrosis (eg: Raraigh_2022). The following publication have been ascertained in the context of this evaluation (PMID: 34782259). Two submitters have cited clinical-significance assessments for this variant to ClinVar after 2014. All submitters classified the variant as pathogenic. Based on the evidence outlined above, the variant was classified as pathogenic. |