Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001909041 | SCV002172703 | pathogenic | not provided | 2023-11-17 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Asn394Argfs*37) in the CYP11B1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in CYP11B1 are known to be pathogenic (PMID: 8506298, 26476331). This variant is present in population databases (rs758714890, gnomAD 0.007%). This premature translational stop signal has been observed in individual(s) with autosomal recessive adrenal hyperplasia (PMID: 1430088). This variant is also known as a 2-bp insertion at codon 394. ClinVar contains an entry for this variant (Variation ID: 1403418). For these reasons, this variant has been classified as Pathogenic. |
Clinical Biochemistry Laboratory, |
RCV002279773 | SCV004190272 | likely pathogenic | Deficiency of steroid 11-beta-monooxygenase | 2023-11-20 | criteria provided, single submitter | clinical testing | ACMG:PVS1 PM2 PP3 |
Baylor Genetics | RCV002279773 | SCV005058663 | pathogenic | Deficiency of steroid 11-beta-monooxygenase | 2024-03-03 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005042487 | SCV005675067 | pathogenic | Deficiency of steroid 11-beta-monooxygenase; Glucocorticoid-remediable aldosteronism | 2024-06-18 | criteria provided, single submitter | clinical testing | |
OMIM | RCV002279773 | SCV000021384 | pathogenic | Deficiency of steroid 11-beta-monooxygenase | 1992-11-01 | no assertion criteria provided | literature only |