Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
ARUP Laboratories, |
RCV000587238 | SCV000603915 | likely benign | not provided | 2023-11-27 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000855647 | SCV000697095 | likely benign | not specified | 2020-08-07 | criteria provided, single submitter | clinical testing | Variant summary: HBB c.220G>A (p.Asp74Asn) results in a conservative amino acid change in the encoded protein sequence. Five of five in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 4.9e-05 in 143240 control chromosomes, predominantly at a frequency of 0.00017 within the African or African-American subpopulation in the gnomAD database (v3 genome dataset). The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. c.220G>A is also known as Hb G-Accra or Hb Korle-Bu when found in isolation, and as Hb C-Harlem or Hb C-Georgetown when found in cis with the Hb S mutation. When present in homozygosity, this variant reportedly does not cause hemoglobinopathy, and is considered an unusual hemoglobin rather than an abnormal/harmful hemoglobin (Boi-Doku_1964, Konotey_1968). In compound heterozygosity with HbS, HbC or beta-thal mutations, the variant of interest reportedly causes no apparent sickness and leads to a sickle-cell trait (when in compound heterozygosity with HbS) rather than sickle-cell disease, HbC disease or beta thalassemia, and does not seem to aggravate the mild status of beta thalassemia heterozygosity (Akl_2009, Chico_2004, Huisman_1997, Konotey_1968, van der Padt_2005). Three publications reported experimental evidence evaluating an impact on protein function, however, none of these studies allow convincing conclusions about the variant effect (Bookchin_1967, Nagel_1993, Ivanova_2001). Two other clinical diagnostic laboratories have submitted clinical-significance assessments for this variant to ClinVar after 2014, without evidence for independent evaluation, and both of them classified the variant as likely benign. Based on the evidence outlined above, the variant was classified as likely benign. |
Quest Diagnostics Nichols Institute San Juan Capistrano | RCV000587238 | SCV001134215 | likely benign | not provided | 2023-04-13 | criteria provided, single submitter | clinical testing | |
Revvity Omics, |
RCV000587238 | SCV004235257 | uncertain significance | not provided | 2023-02-10 | criteria provided, single submitter | clinical testing | |
OMIM | RCV000016449 | SCV000036717 | other | HEMOGLOBIN KORLE-BU | 2017-12-12 | no assertion criteria provided | literature only | |
Natera, |
RCV001826465 | SCV002089212 | likely benign | beta Thalassemia | 2021-01-22 | no assertion criteria provided | clinical testing |