Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
ARUP Laboratories, |
RCV000508345 | SCV000603944 | likely benign | not specified | 2017-01-17 | criteria provided, single submitter | clinical testing | |
Quest Diagnostics Nichols Institute San Juan Capistrano | RCV000985743 | SCV001134220 | benign | not provided | 2021-10-04 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000508345 | SCV002041570 | uncertain significance | not specified | 2021-11-24 | criteria provided, single submitter | clinical testing | Variant summary: HBB c.29C>G (p.Ser10Cys) results in a non-conservative amino acid change located in the Globin domain (IPR000971) of the encoded protein sequence. Three of five in-silico tools predict a benign effect of the variant on protein function. The variant allele was found at a frequency of 4e-06 in 251216 control chromosomes. The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. c.29C>G has been reported in the literature in individuals affected with Hemoglobinopathy (e.g. Goncalves_1994). However, this variant was also found in patients in heterozygous or homozygous state, who have normal hematological values (e.g. Colombo_1985, Malcorra-Azpiazu_1993, Cataldo_2012). These data do not allow any conclusion about variant significance. At least one publication reports experimental evidence evaluating an impact on protein function. These results showed no damaging effect of this variant (Tondo_1974). Two clinical diagnostic laboratories have submitted clinical-significance assessments for this variant to ClinVar after 2014 without evidence for independent evaluation. Both laboratories classified the variant as likely benign. Based on the evidence outlined above, the variant was classified as VUS-possibly benign. |
OMIM | RCV000016556 | SCV000036824 | other | HEMOGLOBIN PORTO ALEGRE | 2000-05-09 | no assertion criteria provided | literature only |