Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000669540 | SCV000794301 | likely pathogenic | Sandhoff disease | 2017-10-05 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000669540 | SCV002134938 | pathogenic | Sandhoff disease | 2021-07-18 | criteria provided, single submitter | clinical testing | This variant has not been reported in the literature in individuals affected with HEXB-related conditions. For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the HEXB protein in which other variant(s) (p.Cys534*) have been determined to be pathogenic (PMID: 29448188, 30075786). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. This variant is not present in population databases (ExAC no frequency). This sequence change creates a premature translational stop signal (p.Asp521Glufs*5) in the HEXB gene. While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 36 amino acid(s) of the HEXB protein. |