Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
LDLR- |
RCV000237707 | SCV000295447 | likely pathogenic | Hypercholesterolemia, familial, 1 | 2016-03-25 | criteria provided, single submitter | literature only | |
Centre de Génétique Moléculaire et Chromosomique, |
RCV000237707 | SCV000503351 | likely pathogenic | Hypercholesterolemia, familial, 1 | 2016-12-16 | criteria provided, single submitter | clinical testing | subjects mutated among 2600 FH index cases screened = 2 , family members = 3 /FH-Fiacenza/Software predictions: Conflicting |
U4M - |
RCV000237707 | SCV000583834 | pathogenic | Hypercholesterolemia, familial, 1 | 2017-03-30 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000781505 | SCV000919587 | pathogenic | Familial hypercholesterolemia | 2024-11-18 | criteria provided, single submitter | clinical testing | Variant summary: LDLR c.1463T>A (p.Ile488Asn) results in a non-conservative amino acid change located in the LDLR class B repeat of the encoded protein sequence. Five of five in-silico tools predict a damaging effect of the variant on protein function. The variant was absent in 251524 control chromosomes. c.1463T>A has been reported in the literature in multiple individuals affected with Familial Hypercholesterolemia (e.g. Garcia-Garcia_2001, Bertolini_2013, Wintjens_2016). Additionally, other missense variants affecting the same codon (I488S, I488T) have been classified on the pathogenic spectrum in ClinVar. These data indicate that the variant is very likely to be associated with disease. To our knowledge, no experimental evidence demonstrating an impact on protein function has been reported. The following publications have been ascertained in the context of this evaluation (PMID: 11668640, 23375686, 26802169). ClinVar contains an entry for this variant (Variation ID: 251856). Based on the evidence outlined above, the variant was classified as pathogenic. |