Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Department Of Genetics, |
RCV000761476 | SCV000891589 | pathogenic | Deficiency of alpha-mannosidase | 2017-12-30 | criteria provided, single submitter | curation | |
Genome- |
RCV000761476 | SCV002014442 | pathogenic | Deficiency of alpha-mannosidase | 2021-09-05 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000761476 | SCV003443116 | pathogenic | Deficiency of alpha-mannosidase | 2022-10-20 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (gnomAD no frequency). ClinVar contains an entry for this variant (Variation ID: 623335). This premature translational stop signal has been observed in individual(s) with an abnormality of the cardiovascular system (PMID: 26633542). This sequence change creates a premature translational stop signal (p.Tyr401*) in the MAN2B1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in MAN2B1 are known to be pathogenic (PMID: 9915946, 22161967). For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV000761476 | SCV005655507 | likely pathogenic | Deficiency of alpha-mannosidase | 2024-02-25 | criteria provided, single submitter | clinical testing |