Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Diagnostics Services |
RCV003448933 | SCV004176728 | uncertain significance | Roussy-Lévy syndrome; Dejerine-Sottas disease; Neuropathy, congenital hypomyelinating, 2 | 2023-12-11 | criteria provided, single submitter | clinical testing | The c.265_270del variant is not present in publicly available population databases like 1000 Genomes, EVS, ExAC, gnomAD, Indian Exome Database or our in-house exome database. This variant has neither been reported in the literature in individuals affected with MPZ-related conditions nor reported to the clinical databases like Human Genome Mutation Database (HGMD), ClinVar or OMIM, in any affected individuals. In-silico pathogenicity prediction programs like MutationTaster2, CADD, Varsome etc predicted this variant to be likely deleterious. This variant is located in a mutational hotspot and non-repeat region of the gene that causes in-frame deletion of 2 amino acids that results in change of protein coding length. |