Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000670133 | SCV000794950 | likely pathogenic | Propionic acidemia | 2017-10-26 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000670133 | SCV000931377 | pathogenic | Propionic acidemia | 2024-04-22 | criteria provided, single submitter | clinical testing | This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 434 of the PCCB protein (p.Ala434Val). The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This missense change has been observed in individual(s) with propionic acidemia (PMID: 24863100). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 554490). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV000670133 | SCV001162960 | pathogenic | Propionic acidemia | 2024-02-08 | criteria provided, single submitter | clinical testing | |
3billion | RCV000670133 | SCV002521852 | pathogenic | Propionic acidemia | 2022-05-22 | criteria provided, single submitter | clinical testing | The variant is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.002%). In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.99; 3Cnet: 0.80). Same nucleotide change resulting in same amino acid change has been previously reported as pathogenic/likely pathogenic with strong evidence (ClinVar ID: VCV000554490). The variant has been observed in multiple (>3) similarly affected unrelated individuals (PMID:24863100). Therefore, this variant is classified as pathogenic according to the recommendation of ACMG/AMP guideline. |
Natera, |
RCV000670133 | SCV001454528 | pathogenic | Propionic acidemia | 2020-09-16 | no assertion criteria provided | clinical testing |