Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV000165222 | SCV000215936 | pathogenic | Hereditary cancer-predisposing syndrome | 2017-11-10 | criteria provided, single submitter | clinical testing | The p.E661* pathogenic mutation (also known as c.1981G>T), located in coding exon 11 of the PMS2 gene, results from a G to T substitution at nucleotide position 1981. This changes the amino acid from a glutamic acid to a stop codon within coding exon 11. This mutation was observed in two individuals diagnosed with colon cancer in their 30's and tumor studies for both individuals showed isolated loss of PMS2 protein on IHC (Gulati, S et al. Gastrointest Cancer Res. 2011 Sep;4(5-6):188-90; Vaughn, CP et al. Hum Mutat. 2010 May;31(5):588-93). One of the tumors was also found to be MSI-High (Gulati, S et al. Gastrointest Cancer Res. 2011 Sep;4(5-6):188-90). In addition to the clinical data presented in the literature, this alteration is expected to result in loss of function by premature protein truncation or nonsense-mediated mRNA decay. As such, this alteration is interpreted as a disease-causing mutation. |
Labcorp Genetics |
RCV001201579 | SCV001372655 | pathogenic | Hereditary nonpolyposis colorectal neoplasms | 2024-10-24 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Glu661*) in the PMS2 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in PMS2 are known to be pathogenic (PMID: 21376568, 24362816). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with colorectal cancer (PMID: 20205264, 22295133, 28514183). ClinVar contains an entry for this variant (Variation ID: 185743). For these reasons, this variant has been classified as Pathogenic. |
Myriad Genetics, |
RCV003454403 | SCV004187690 | pathogenic | Lynch syndrome 4 | 2023-09-21 | criteria provided, single submitter | clinical testing | This variant is considered pathogenic. This variant creates a termination codon and is predicted to result in premature protein truncation. |
Baylor Genetics | RCV003454403 | SCV004207900 | pathogenic | Lynch syndrome 4 | 2022-04-14 | criteria provided, single submitter | clinical testing | |
Gene |
RCV004721281 | SCV005326984 | pathogenic | not provided | 2024-03-18 | criteria provided, single submitter | clinical testing | Nonsense variant predicted to result in protein truncation or nonsense mediated decay in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); Truncating variants in this gene are considered pathogenic by a well-established clinical consortium and/or database; This variant is associated with the following publications: (PMID: 24362816, 21376568, 28514183, 20205264, 22295133, 25691505) |