Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Prevention |
RCV000721462 | SCV000852532 | uncertain significance | not provided | 2017-10-20 | criteria provided, single submitter | clinical testing | |
All of Us Research Program, |
RCV003999834 | SCV004820481 | uncertain significance | Malignant hyperthermia, susceptibility to, 1 | 2023-03-23 | criteria provided, single submitter | clinical testing | This missense variant replaces histidine with arginine at codon 865 of the RYR1 protein. Computational prediction suggests that this variant may have deleterious impact on protein structure and function (internally defined REVEL score threshold >= 0.7, PMID: 27666373). To our knowledge, functional studies have not been reported for this variant. This variant has been reported in an individual affected with a suspected malignant hyperthermia event (PMID: 31559918). This variant has not been identified in the general population by the Genome Aggregation Database (gnomAD). The available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |