Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV002250353 | SCV002520659 | likely pathogenic | Monogenic diabetes | 2022-05-03 | reviewed by expert panel | curation | The c.1506_1507dupCT variant in the HNF1 homeobox A gene, HNF1A, causes a frameshift in the protein at codon 503 (NM_000545.8), adding 29 novel amino acids before encountering a stop codon (p.Tyr503SerfsTer29). This variant, located in biologically-relevant exon 8 of 10, is predicted to lead to nonsense mediated decay in a gene in which loss-of-function is an established disease mechanism (PVS1; PMID: 23348805). This variant is also absent from gnomAD v2.1.1 (PM2_Supporting). In summary, c.1506_1507dupCT meets the criteria to be classified as likely pathogenic for monogenic diabetes. ACMG/AMP criteria applied, as specified by the ClinGen MDEP (specification version 1.1, approved 9/30/2021): PVS1, PM2_Supporting. |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000030483 | SCV000053153 | likely pathogenic | Maturity-onset diabetes of the young type 3 | 2011-08-18 | criteria provided, single submitter | curation | Converted during submission to Likely pathogenic. |
Clinical Genomics, |
RCV002463433 | SCV002604940 | uncertain risk allele | Maturity onset diabetes mellitus in young | criteria provided, single submitter | research | Mutations in HNF1A gene can predispose to MODY3. It is associated with both micro and macrovascular complications of diabetes, especially cardiovascular complications. Associated with glucosuria. May respond well to sulfonylureas. However, more evidence is required to confer the association of this particular variant rs193922582 with MODY3. |