Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Broad Center for Mendelian Genomics, |
RCV001248949 | SCV001422728 | uncertain significance | Maturity-onset diabetes of the young type 3 | 2020-01-22 | criteria provided, single submitter | curation | The p.Arg114Cys variant in HNF1A has not been previously reported in individuals with maturity-onset diabetes of the young and has been identified in 0.01% (3/30610) of South Asian chromosomes by the Genome Aggregation Database (gnomAD, http://gnomad.broadinstitute.org; dbSNP rs774996577). Computational prediction tools and conservation analyses suggest that this variant may impact the protein, though this information is not predictive enough to determine pathogenicity. In summary, the clinical significance of the p.Arg114Cys variant is uncertain. ACMG/AMP Criteria applied: BS1, PP3 (Richards 2015). |
Molecular Genetics, |
RCV002051926 | SCV002318386 | uncertain significance | Maturity onset diabetes mellitus in young | criteria provided, single submitter | clinical testing | ||
Clinical Genomics, |
RCV002051926 | SCV002758781 | likely risk allele | Maturity onset diabetes mellitus in young | criteria provided, single submitter | research | Mutations in HNF1A gene can predispose to MODY3. It is associated with both micro and macrovascular complications of diabetes, especially cardiovascular complications. Associated with glucosuria. May respond well to sulfonylureas. However, more evidence is required to confer the association of this particular variant rs774996577 with MODY3. |