Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV002250357 | SCV002520653 | uncertain significance | Monogenic diabetes | 2022-05-02 | reviewed by expert panel | curation | The c.734G>T variant in the HNF1 homeobox A gene, HNF1A, causes an amino acid change of glycine to valine at codon 245 (p.Gly245Val) of NM_000545.8. This variant is located within a conserved region of the DNA binding domain (codons 107-174 and 201-280) of HNF1A, which is defined as critical for the protein’s function by the ClinGen MDEP (PM1_Supporting). This variant is also absent from gnomAD v2.1.1 (PM2_Supporting). This variant is predicted to be deleterious by computational evidence, with a REVEL score of 0.956, which is greater than the MDEP VCEP threshold of 0.70 (PP3). Lastly, this variant was identified in an individual with a clinical history highly specific for HNF1A-MODY (MODY probability calculator result >50%, negative antibodies, and low hsCRP; HNF4A not tested, but low hsCRP is specific to HNF1A vs. HNF4A) (PP4_Moderate; PMID: 30181854). Another missense variant, c.733G>A (p.Gly245Arg) has been classified as a VUS by the ClinGen MDEP; therefore, PM5 will not be applied. In summary, c.734G>T meets the criteria to be classified as a variant of uncertain significance for monogenic diabetes. ACMG/AMP criteria applied, as specified by the ClinGen MDEP (specification version 1.1, approved 9/30/2021): PM1_Supporting, PM2_Supporting, PP3, PP4_Moderate. |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV000030510 | SCV000053181 | likely pathogenic | Maturity-onset diabetes of the young type 3 | 2011-08-18 | criteria provided, single submitter | curation | Converted during submission to Likely pathogenic. |
Athena Diagnostics | RCV000993273 | SCV001146110 | uncertain significance | not provided | 2019-03-22 | criteria provided, single submitter | clinical testing |