Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Broad Center for Mendelian Genomics, |
RCV001248890 | SCV001422570 | uncertain significance | Maturity-onset diabetes of the young type 3 | 2020-01-22 | criteria provided, single submitter | curation | The p.Gly288Trp variant in HNF1A has been reported in at least 1 individual with maturity-onset diabetes of the young (PMID: 25306193), and has been identified in 0.030% (3/9944) of Ashkenazi Jewish chromosomes and 0.011% (13/122942) of European (non-Finnish) chromosomes by the Genome Aggregation Database (gnomAD, http://gnomad.broadinstitute.org; dbSNP rs539507291). Computational prediction tools and conservation analyses suggest that this variant may impact the protein, though this information is not predictive enough to determine pathogenicity. In summary, while the clinical significance of the p.Gly288Trp variant is uncertain, these data suggest that it is more likely to be benign. ACMG/AMP Criteria applied: BA1, PP3 (Richards 2015). |
Ambry Genetics | RCV002375309 | SCV002684216 | likely benign | Maturity onset diabetes mellitus in young | 2021-09-03 | criteria provided, single submitter | clinical testing | This alteration is classified as likely benign based on a combination of the following: seen in unaffected individuals, population frequency, intact protein function, lack of segregation with disease, co-occurrence, RNA analysis, in silico models, amino acid conservation, lack of disease association in case-control studies, and/or the mechanism of disease or impacted region is inconsistent with a known cause of pathogenicity. |
Labcorp Genetics |
RCV002568693 | SCV003257362 | likely benign | not provided | 2024-12-02 | criteria provided, single submitter | clinical testing |