Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000644114 | SCV000765804 | likely pathogenic | Tuberous sclerosis 2 | 2018-03-05 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (ExAC no frequency). A different missense substitution at this codon (p.Thr147Arg) has been reported in an individual affected with tuberous sclerosis (PMID: 27859028). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of missense changes on protein structure and function do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C0"). This variant has been reported to be de novo in an individual affected with tuberous sclerosis (Invitae). This sequence change replaces threonine with lysine at codon 147 of the TSC2 protein (p.Thr147Lys). The threonine residue is highly conserved and there is a moderate physicochemical difference between threonine and lysine. |