Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000817306 | SCV000957858 | uncertain significance | Tuberous sclerosis 2 | 2023-12-13 | criteria provided, single submitter | clinical testing | This sequence change replaces threonine, which is neutral and polar, with isoleucine, which is neutral and non-polar, at codon 317 of the TSC2 protein (p.Thr317Ile). This variant is not present in population databases (gnomAD no frequency). This variant has not been reported in the literature in individuals affected with TSC2-related conditions. ClinVar contains an entry for this variant (Variation ID: 660174). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt TSC2 protein function with a negative predictive value of 95%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Gene |
RCV002298787 | SCV002588355 | uncertain significance | not provided | 2022-04-28 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Has not been previously published as pathogenic or benign to our knowledge; This variant is associated with the following publications: (PMID: 18466115) |
Ambry Genetics | RCV002372313 | SCV002688416 | uncertain significance | Hereditary cancer-predisposing syndrome | 2022-05-04 | criteria provided, single submitter | clinical testing | The p.T317I variant (also known as c.950C>T), located in coding exon 9 of the TSC2 gene, results from a C to T substitution at nucleotide position 950. The threonine at codon 317 is replaced by isoleucine, an amino acid with similar properties. This amino acid position is well conserved in available vertebrate species. In addition, the in silico prediction for this alteration is inconclusive. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
All of Us Research Program, |
RCV004803262 | SCV005427059 | uncertain significance | Tuberous sclerosis syndrome | 2024-08-06 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004735819 | SCV005365737 | uncertain significance | TSC2-related disorder | 2024-03-29 | no assertion criteria provided | clinical testing | The TSC2 c.950C>T variant is predicted to result in the amino acid substitution p.Thr317Ile. To our knowledge, this variant has not been reported in the literature or in a large population database (http://gnomad.broadinstitute.org), indicating this variant is rare. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |