Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001851935 | SCV002259721 | pathogenic | not provided | 2024-01-19 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with glutamine, which is neutral and polar, at codon 356 of the TYRP1 protein (p.Arg356Gln). This variant is present in population databases (rs281865424, gnomAD 0.01%). This missense change has been observed in individuals with oculocutaneous albinism (PMID: 16704458, 21739261, 28266639). This variant is also known as c.1066G>A. ClinVar contains an entry for this variant (Variation ID: 17596). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt TYRP1 protein function with a positive predictive value of 80%. For these reasons, this variant has been classified as Pathogenic. |
Fulgent Genetics, |
RCV002476990 | SCV002777440 | likely pathogenic | Oculocutaneous albinism type 3; MELANESIAN BLOND HAIR | 2024-06-16 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV003390690 | SCV004112004 | pathogenic | TYRP1-related disorder | 2023-05-30 | criteria provided, single submitter | clinical testing | The TYRP1 c.1067G>A variant is predicted to result in the amino acid substitution p.Arg356Gln. This variant has been reported in the homozygous and compound heterozygous state in individuals with oculocutaneous albinism (Rooryck et al. 2006. PubMed ID: 16704458; Shahzad et al. 2017. PubMed ID: 28266639; Zhang et al. 2011. PubMed ID: 21739261). This variant is reported in 0.0098% of alleles in individuals of South Asian descent in gnomAD (http://gnomad.broadinstitute.org/variant/9-12702424-G-A). Given the evidence, we interpret c.1067G>A (p.Arg356Gln) as pathogenic. |
Gene |
RCV001851935 | SCV005396390 | uncertain significance | not provided | 2024-05-01 | criteria provided, single submitter | clinical testing | Observed with a second TYRP1 variant in unrelated patients in published literature, but it is not known whether the variants occurred on the same (in cis) or on different (in trans) chromosomes in some cases (PMID: 16704458, 21739261, 34838614); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 23862152, 28661582, 37956964, 35547362, 38542347, 30868578, 28266639, 34838614, 16704458, 21739261) |
OMIM | RCV000019162 | SCV000039450 | pathogenic | Oculocutaneous albinism type 3 | 2006-06-01 | no assertion criteria provided | literature only | |
University of Washington Center for Mendelian Genomics, |
RCV000755096 | SCV000882914 | likely pathogenic | Nonsyndromic Oculocutaneous Albinism | 2017-03-07 | no assertion criteria provided | research |