Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ce |
RCV003436841 | SCV004164570 | uncertain significance | not provided | 2022-10-01 | criteria provided, single submitter | clinical testing | GSR: PVS1:Strong |
Revvity Omics, |
RCV003492877 | SCV004235224 | uncertain significance | Hemolytic anemia due to glutathione reductase deficiency | 2023-03-30 | criteria provided, single submitter | clinical testing | |
Neuberg Centre For Genomic Medicine, |
RCV003492877 | SCV005373673 | likely pathogenic | Hemolytic anemia due to glutathione reductase deficiency | 2023-05-20 | criteria provided, single submitter | clinical testing | The observed stop gained variant c.94G>T(p.Glu32Ter) in GSR gene has not been reported previously as a pathogenic variant nor as a benign variant, to our knowledge. The c.94G>T variant has 0.04% allele frequency in gnomAD Exomes. Computational evidence (Mutation Taster - Disease causing) predicts damaging effect on protein structure and function for this variant.This variant is predicted to cause loss of normal protein function through protein truncation. Loss of function variants have been previously reported to be disease causing (Kamerbeek NM, et al., 2007). For these reasons, this variant has been classified as Likely Pathogenic. In the absence of another reportable variant, the molecular diagnosis is not confirmed. |