Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001533152 | SCV002240707 | pathogenic | Familial hemiplegic migraine | 2022-10-24 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Experimental studies have shown that this missense change affects ATP1A2 function (PMID: 19372756, 21398422). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ATP1A2 protein function. ClinVar contains an entry for this variant (Variation ID: 12922). This missense change has been observed in individuals with familial hemiplegic migraine (PMID: 15459825, 21398422). It has also been observed to segregate with disease in related individuals. This variant is not present in population databases (gnomAD no frequency). This sequence change replaces glycine, which is neutral and non-polar, with arginine, which is basic and polar, at codon 301 of the ATP1A2 protein (p.Gly301Arg). |
OMIM | RCV000013785 | SCV000034032 | pathogenic | Migraine, familial hemiplegic, 2 | 2004-09-01 | no assertion criteria provided | literature only | |
Gene |
RCV001533152 | SCV001748970 | not provided | Familial hemiplegic migraine | no assertion provided | literature only | Severe phenotype reported |