Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000001821 | SCV002135188 | uncertain significance | Orthostatic hypotension 1 | 2020-11-14 | criteria provided, single submitter | clinical testing | This sequence change replaces aspartic acid with glutamic acid at codon 114 of the DBH protein (p.Asp114Glu). The aspartic acid residue is highly conserved and there is a small physicochemical difference between aspartic acid and glutamic acid. This variant is present in population databases (rs77576840, ExAC 0.01%). This variant has been observed in individual(s) with dopamine beta-hydroxylase deficiency (PMID: 11857564). In at least one individual the data is consistent with the variant being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 1751). Experimental studies have shown that this variant affects DBH protein function (PMID: 21209083). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
OMIM | RCV000001821 | SCV000021977 | pathogenic | Orthostatic hypotension 1 | 2002-03-01 | no assertion criteria provided | literature only | |
Gene |
RCV000001821 | SCV000256550 | not provided | Orthostatic hypotension 1 | no assertion provided | literature only | Abnormal protein retained in cell, suggesting abnormal trafficking & secretion [Kim et al 2011] |