Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001385681 | SCV001585627 | pathogenic | not provided | 2023-03-08 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. ClinVar contains an entry for this variant (Variation ID: 1072852). This premature translational stop signal has been observed in individual(s) with congenital stationary night blindness (PMID: 25307992, 26628857). It has also been observed to segregate with disease in related individuals. This variant is present in population databases (rs764476239, gnomAD 0.01%). This sequence change creates a premature translational stop signal (p.Arg446*) in the GRM6 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in GRM6 are known to be pathogenic (PMID: 15781871, 16622103, 22008250). |
3billion | RCV001810046 | SCV002058188 | pathogenic | Congenital stationary night blindness 1B | 2022-01-03 | criteria provided, single submitter | clinical testing | Stop-gained (nonsense): predicted to result in a loss or disruption of normal protein function through nonsense-mediated decay (NMD) or protein truncation. Multiple pathogenic variants are reported downstream of the variant (PVS1_VS).The variant has been reported to be associated with GRM6 related disorder (ClinVar ID: VCV001072852, PMID:25307992).It is observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.000016, PM2_M). Therefore, this variant is classified as pathogenic according to the recommendation of ACMG/AMP guideline. |