Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion | RCV001029845 | SCV002058488 | uncertain significance | Retinitis pigmentosa 10 | 2022-01-03 | criteria provided, single submitter | clinical testing | The variant observed at an extremely low frequency in the gnomAD v2.1.1 dataset (total allele frequency: 0.000004, PM2_M). In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.864, PP3_P). A missense variant is a common mechanism associated with Retinitis pigmentosa 10 (PP2_P). Therefore, this variant is classified as uncertain significance according to the recommendation of ACMG/AMP guideline. |
Labcorp Genetics |
RCV003768928 | SCV004667016 | uncertain significance | not provided | 2023-09-15 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with serine, which is neutral and polar, at codon 548 of the IMPDH1 protein (p.Gly548Ser). This variant is present in population databases (no rsID available, gnomAD 0.0009%). This variant has not been reported in the literature in individuals affected with IMPDH1-related conditions. ClinVar contains an entry for this variant (Variation ID: 829898). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Bioscientia Institut fuer Medizinische Diagnostik Gmb |
RCV001029845 | SCV001192631 | uncertain significance | Retinitis pigmentosa 10 | 2019-09-12 | no assertion criteria provided | clinical testing |