Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Blueprint Genetics | RCV001075270 | SCV001240885 | uncertain significance | Retinal dystrophy | 2017-09-01 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001209281 | SCV001380707 | uncertain significance | not provided | 2020-02-22 | criteria provided, single submitter | clinical testing | This variant has not been reported in the literature in individuals with IMPDH1-related conditions. This variant is not present in population databases (ExAC no frequency). This sequence change falls in intron 16 of the IMPDH1 gene. It does not directly change the encoded amino acid sequence of the IMPDH1 protein, but it affects a nucleotide within the consensus splice site of the intron. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Nucleotide substitutions within the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site, but this prediction has not been confirmed by published transcriptional studies. |