Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000493275 | SCV000582094 | uncertain significance | not provided | 2024-08-29 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 31847883) |
Labcorp Genetics |
RCV001368294 | SCV001564683 | uncertain significance | Long QT syndrome | 2024-06-03 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with aspartic acid, which is acidic and polar, at codon 222 of the KCNJ5 protein (p.Gly222Asp). This variant is present in population databases (rs746522890, gnomAD 0.003%). This missense change has been observed in individual(s) with KCNJ5-related conditions (PMID: 31847883). ClinVar contains an entry for this variant (Variation ID: 429508). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt KCNJ5 protein function with a positive predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Fulgent Genetics, |
RCV002489207 | SCV002798277 | uncertain significance | Long QT syndrome 13; Familial hyperaldosteronism type III | 2022-01-11 | criteria provided, single submitter | clinical testing |