Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003628573 | SCV004453715 | pathogenic | Pyruvate dehydrogenase E1-beta deficiency | 2023-04-07 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Tyr77*) in the PDHB gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in PDHB are known to be pathogenic (PMID: 21914562, 25356417). For these reasons, this variant has been classified as Pathogenic. This variant has not been reported in the literature in individuals affected with PDHB-related conditions. This variant is not present in population databases (gnomAD no frequency). |