Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV002300923 | SCV002588196 | pathogenic | not provided | 2022-04-28 | criteria provided, single submitter | clinical testing | Published functional studies demonstrate that this variant causes aberrant splicing (Ahting et al., 2015); Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 25918518) |
Labcorp Genetics |
RCV003101709 | SCV003524646 | uncertain significance | Multiple mitochondrial dysfunctions syndrome 1 | 2022-08-19 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. This variant has been observed in individual(s) with multiple mitochondrial dysfunctions syndrome (PMID: 25918518). This variant is present in population databases (rs559190059, gnomAD 0.007%). This sequence change falls in intron 3 of the NFU1 gene. It does not directly change the encoded amino acid sequence of the NFU1 protein. It affects a nucleotide within the consensus splice site. |
OMIM | RCV003101709 | SCV005201138 | pathogenic | Multiple mitochondrial dysfunctions syndrome 1 | 2024-09-12 | no assertion criteria provided | literature only |