Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001864914 | SCV002126813 | uncertain significance | Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1, open angle, E | 2024-04-11 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamine, which is neutral and polar, with lysine, which is basic and polar, at codon 530 of the OPTN protein (p.Gln530Lys). This variant is present in population databases (rs759605171, gnomAD 0.009%). This missense change has been observed in individual(s) with amyotrophic lateral sclerosis (PMID: 29525178). ClinVar contains an entry for this variant (Variation ID: 1360254). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt OPTN protein function with a negative predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV002397798 | SCV002705683 | uncertain significance | Inborn genetic diseases | 2020-03-21 | criteria provided, single submitter | clinical testing | The p.Q530K variant (also known as c.1588C>A), located in coding exon 12 of the OPTN gene, results from a C to A substitution at nucleotide position 1588. The glutamine at codon 530 is replaced by lysine, an amino acid with similar properties. This alteration was noted in a single individual with a clinical diagnosis of amyotrophic lateral sclerosis; however, it is unknown if this alteration was detected in a heterozygous, compound heterozygous, or homozygous state (Lamp M et al. Neurobiol. Aging, 2018 06;66:179.e5-179.e16). This amino acid position is well conserved in available vertebrate species. In addition, this alteration is predicted to be tolerated by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Prevention |
RCV004536383 | SCV004119474 | uncertain significance | OPTN-related disorder | 2023-03-14 | criteria provided, single submitter | clinical testing | The OPTN c.1588C>A variant is predicted to result in the amino acid substitution p.Gln530Lys. This variant was reported in an individual with sporadic amyotrophic lateral sclerosis who also carried an in-frame deletion in the HNRNPA1 gene (Lamp et al 2018. PubMed ID: 29525178). This variant is reported in 0.0087% of alleles in individuals of Latino descent in gnomAD (http://gnomad.broadinstitute.org/variant/10-13175557-C-A). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |