Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetics and Molecular Pathology, |
RCV002466940 | SCV002761894 | likely pathogenic | Polycystic kidney disease, adult type | 2021-07-07 | criteria provided, single submitter | clinical testing | 2xPP, 2xPM |
Prevention |
RCV003984264 | SCV004800258 | likely pathogenic | PKD1-related disorder | 2024-02-27 | no assertion criteria provided | clinical testing | The PKD1 c.11257C>G variant is predicted to result in the amino acid substitution p.Arg3753Gly. This variant was reported in an individual with autosomal dominant polycystic kidney disease (ADPKD) (Kinoshita et al. 2016. PubMed ID: 27835667, Suppl. Table S6). In addition, we have also found this variant in the heterozygous state in a patient with polycystic kidney disease at PreventionGenetics. Of note, different substitutions at the same codon have been reported in individuals with autosomal dominant polycystic kidney disease (ADPKD) (p.Arg3753Trp at Chang et al. 2013. PubMed ID: 23985799; p.Arg3753Gln at Rossetti et al. 2007. PubMed ID: 17582161; p.Arg3753Leu at Rossetti et al. 2012. PubMed ID: 22383692). The c.11257C>G (p.Arg3753Gly) variant has not been reported in a large population database (http://gnomad.broadinstitute.org), indicating this variant is rare. This variant is interpreted as likely pathogenic. |