Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV004593261 | SCV005079339 | pathogenic | not provided | 2023-07-11 | criteria provided, single submitter | clinical testing | Published functional studies demonstrate a damaging effect on the interaction between CCM1 and CCM2 proteins, reducing the stability of the ternary CCM complex (Bergametti et al., 2020); Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 35128084, 25525273, 23595507, 31937560) |
OMIM | RCV003319556 | SCV004023348 | pathogenic | Cerebral cavernous malformation 2 | 2023-08-04 | no assertion criteria provided | literature only |