Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV000004333 | SCV000914923 | uncertain significance | Vanishing white matter disease | 2018-11-28 | criteria provided, single submitter | clinical testing | The EIF2B4 c.1067G>A (p.Arg356Gln) missense variant has been reported in three individuals, including a sibling pair, affected with white matter vanishing disease, all in a compound heterozygous state with a missense variant. The variant was present in one unaffected parent in a heterozygous state, absent from 120 control chromosomes and is reported at a frequency of 0.000012 in the Total population of the Genome Aggregation Database. Based on the limited evidence, the p.Arg356Gln variant is classified as a variant of unknown significance but suspicious for pathogenicity for childhood ataxia with central nervous system hypomyelination/vanishing white matter. This variant was observed by ICSL as part of a predisposition screen in an ostensibly healthy population. |
OMIM | RCV003221393 | SCV000024504 | pathogenic | Leukoencephalopathy with vanishing white matter 4 | 2002-02-01 | no assertion criteria provided | literature only |