Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Illumina Laboratory Services, |
RCV000778612 | SCV000914922 | uncertain significance | Vanishing white matter disease | 2018-10-25 | criteria provided, single submitter | clinical testing | The EIF2B4 c.1502C>T (p.Thr501Met) variant is a missense variant that has been reported in single study and is found in one individual with leukoencephalopathy with vanishing white matter in a compound heterozygous state with a missense variant (Zhang et al. 2015). The p.Thr501Met variant is inherited from the unaffected father. The p.Thr501Met variant is absent from 100 controls and is found at a frequency of 0.000027 in the European (non-Finnish) population of the Genome Aggregation Database. Based on the limited evidence, the p.Thr501Met variant is classified as a variant of unknown significance but suspicious for pathogenicity for childhood ataxia with central nervous system hypomyelination/vanishing white matter. This variant was observed by ICSL as part of a predisposition screen in an ostensibly healthy population. |
Gene |
RCV004588240 | SCV005080570 | likely pathogenic | not provided | 2023-10-20 | criteria provided, single submitter | clinical testing | Reported using alternate nomenclature (c.1565C>T, p.T522M) with a variant on the opposite allele (in trans) in a patient with vanishing white matter disease in published literature (PMID: 25761052); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 34745209, 25761052) |