Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001384844 | SCV001584494 | pathogenic | Seizures, benign familial infantile, 3; Developmental and epileptic encephalopathy, 11 | 2020-08-14 | criteria provided, single submitter | clinical testing | This sequence change replaces valine with leucine at codon 423 of the SCN2A protein (p.Val423Leu). The valine residue is highly conserved and there is a small physicochemical difference between valine and leucine. This variant is not present in population databases (ExAC no frequency). This variant has been observed in individual(s) with Ohtahara syndrome (PMID: 28379373). In at least one individual the variant was observed to be de novo. Experimental studies have shown that this variant affects SCN2A protein function (PMID: 28379373). For these reasons, this variant has been classified as Pathogenic. |