Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001924833 | SCV002155433 | uncertain significance | Neurofibromatosis, type 1 | 2021-05-27 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Nucleotide substitutions within the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site, but this prediction has not been confirmed by published transcriptional studies. This variant has not been reported in the literature in individuals with NF1-related conditions. This variant is not present in population databases (ExAC no frequency). This sequence change falls in intron 27 of the NF1 gene. It does not directly change the encoded amino acid sequence of the NF1 protein. It affects a nucleotide within the consensus splice site of the intron. |
Ce |
RCV004809689 | SCV005435591 | uncertain significance | not provided | 2024-09-01 | criteria provided, single submitter | clinical testing | NF1: PM2, PP3, PP4 |
Prevention |
RCV004552077 | SCV004723256 | uncertain significance | NF1-related disorder | 2023-10-23 | no assertion criteria provided | clinical testing | The NF1 c.3708+3_3708+6delAAGT variant is predicted to result in an intronic deletion. To our knowledge, this variant has not been reported in the literature or in a large population database (http://gnomad.broadinstitute.org), indicating this variant is rare. However, other intronic variants predicted to affect splicing at the same donor site have been reported in patients with features consistent with neurofibromatosis type 1 (c.3708+3A>T, c.3708+5G>A, Assunto et al. 2019. PubMed ID: 31730495, Koster et al. 2021. PubMed ID: 34782607). Although we suspect that this variant may be pathogenic, at this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |