Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV000492202 | SCV000581257 | pathogenic | Hereditary cancer-predisposing syndrome | 2014-10-09 | criteria provided, single submitter | clinical testing | The c.3871-2A>G intronic pathogenic mutation results from an A to G substitution two nucleotides upstream from coding exon 29 of the NF1 gene. This mutation has been detected in an individual meeting NIH diagnostic criteria for Neurofibromatosis type 1 (NF1) and is predicted at the mRNA level to induce the skipping of exon 23 (r.3871_3974del104) (Sabbagh A et al. Hum. Mutat., 2013 Nov;34:1510-8). In addition to the clinical data presented in the literature, alterations that disrupt the canonical splice site are expected to cause aberrant splicing, resulting in an abnormal protein or a transcript that is subject to nonsense-mediated mRNA decay. As such, this alteration is classified as a disease-causing mutation. |
Labcorp Genetics |
RCV000560336 | SCV000628552 | pathogenic | Neurofibromatosis, type 1 | 2024-01-26 | criteria provided, single submitter | clinical testing | This sequence change affects an acceptor splice site in intron 28 of the NF1 gene. It is expected to disrupt RNA splicing. Variants that disrupt the donor or acceptor splice site typically lead to a loss of protein function (PMID: 16199547), and loss-of-function variants in NF1 are known to be pathogenic (PMID: 10712197, 23913538). This variant is not present in population databases (gnomAD no frequency). Disruption of this splice site has been observed in individuals with neurofibromatosis type 1 (PMID: 21520333, 23913538; Invitae). ClinVar contains an entry for this variant (Variation ID: 428953). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. For these reasons, this variant has been classified as Pathogenic. |
Genome- |
RCV000560336 | SCV002560003 | pathogenic | Neurofibromatosis, type 1 | 2022-03-15 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV002356808 | SCV002620517 | pathogenic | Hereditary cancer-predisposing syndrome; Cardiovascular phenotype | 2020-04-10 | criteria provided, single submitter | clinical testing | The c.3871-2A>G intronic pathogenic mutation results from an A to G substitution two nucleotides upstream from coding exon 29 of the NF1 gene. This mutation has been detected in an individual meeting NIH diagnostic criteria for Neurofibromatosis type 1 (NF1) and is predicted at the mRNA level to induce the skipping of exon 23 (r.3871_3974del104) (Sabbagh A et al. Hum. Mutat., 2013 Nov;34:1510-8). In addition to the clinical data presented in the literature, alterations that disrupt the canonical splice site are expected to cause aberrant splicing, resulting in an abnormal protein or a transcript that is subject to nonsense-mediated mRNA decay. As such, this alteration is classified as a disease-causing mutation. |
Gene |
RCV004800427 | SCV005421418 | pathogenic | not provided | 2024-06-03 | criteria provided, single submitter | clinical testing | Canonical splice site variant predicted to result in a null allele in a gene for which loss of function is a known mechanism of disease; Not observed at significant frequency in large population cohorts (gnomAD); This variant is associated with the following publications: (PMID: 16199547, 10712197, 23913538, 31573083) |