Total submissions: 7
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000632493 | SCV000753678 | likely benign | Neurofibromatosis, type 1 | 2024-08-27 | criteria provided, single submitter | clinical testing | |
Gene |
RCV000681301 | SCV000808763 | uncertain significance | not provided | 2018-05-18 | criteria provided, single submitter | clinical testing | This variant is denoted NF1 c.4098C>G at the cDNA level, p.His1366Gln (H1366Q) at the protein level, and results in the change of a Histidine to a Glutamine (CAC>CAG). This variant has not, to our knowledge, been published in the literature as a pathogenic or benign germline variant. NF1 His1366Gln was not observed in large population cohorts (Lek 2016). This variant is located in the GTPase activating protein domain (Thomas 2012, Luo 2014). In silico analysis, which includes protein predictors and evolutionary conservation, supports a deleterious effect. Based on currently available evidence, it is unclear whether NF1 His1366Gln is a pathogenic or benign variant. We consider it to be a variant of uncertain significance. |
Ambry Genetics | RCV002319063 | SCV001183520 | uncertain significance | Hereditary cancer-predisposing syndrome; Cardiovascular phenotype | 2024-03-09 | criteria provided, single submitter | clinical testing | The p.H1366Q variant (also known as c.4098C>G), located in coding exon 30 of the NF1 gene, results from a C to G substitution at nucleotide position 4098. The histidine at codon 1366 is replaced by glutamine, an amino acid with highly similar properties. This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Genome- |
RCV000632493 | SCV002560379 | uncertain significance | Neurofibromatosis, type 1 | 2022-03-15 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV004568381 | SCV005052208 | uncertain significance | Juvenile myelomonocytic leukemia | 2024-03-03 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV005019050 | SCV005646746 | uncertain significance | Neurofibromatosis, familial spinal; Juvenile myelomonocytic leukemia; Neurofibromatosis, type 1; Neurofibromatosis-Noonan syndrome; Café-au-lait macules with pulmonary stenosis | 2024-04-22 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004547784 | SCV004712756 | uncertain significance | NF1-related disorder | 2023-11-21 | no assertion criteria provided | clinical testing | The NF1 c.4098C>G variant is predicted to result in the amino acid substitution p.His1366Gln. To our knowledge, this variant has not been reported in the literature or in a large population database (http://gnomad.broadinstitute.org), indicating this variant is rare. This variant is interpreted as uncertain in ClinVar (https://www.ncbi.nlm.nih.gov/clinvar/variation/527583/). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |