Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000034588 | SCV002013368 | pathogenic | not provided | 2021-05-03 | criteria provided, single submitter | clinical testing | Canonical splice site variant predicted to result in a null allele in a gene for which loss-of-function is a known mechanism of disease; Observed in an individual via exome sequencing for cancer-susceptibility syndromes in participants with atherosclerosis phenotypes (Johnston et al., 2012); Not observed in large population cohorts (Lek et al., 2016); This variant is associated with the following publications: (PMID: 22703879) |
Labcorp Genetics |
RCV003597961 | SCV004552030 | pathogenic | Neurofibromatosis, type 1 | 2023-05-25 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. ClinVar contains an entry for this variant (Variation ID: 41676). Disruption of this splice site has been observed in individuals with NF1-related conditions (PMID: 21354044, 22190595). The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This sequence change affects a donor splice site in intron 7 of the NF1 gene. It is expected to disrupt RNA splicing. Variants that disrupt the donor or acceptor splice site typically lead to a loss of protein function (PMID: 16199547), and loss-of-function variants in NF1 are known to be pathogenic (PMID: 10712197, 23913538). |
Biesecker Lab/Clinical Genomics Section, |
RCV000034588 | SCV000043384 | no known pathogenicity | not provided | 2012-07-13 | no assertion criteria provided | research | Converted during submission to Benign. |
Genomic Diagnostic Laboratory, |
RCV000202947 | SCV000257764 | benign | not specified | 2015-06-18 | flagged submission | clinical testing |