Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ce |
RCV000512688 | SCV000609353 | uncertain significance | not provided | 2019-12-01 | criteria provided, single submitter | clinical testing | |
Victorian Clinical Genetics Services, |
RCV001089980 | SCV001245034 | uncertain significance | Muscular dystrophy-dystroglycanopathy (congenital with brain and eye anomalies), type A1 | 2018-12-16 | criteria provided, single submitter | clinical testing | A heterozygous missense variant, NM_007171.3(POMT1):c.677T>C, has been identified in exon 8 of 20 of the POMT1 gene. This variant is predicted to result in an amino acid change of leucione to proline at position 226 of the protien, NP_009102.3(POMT1)p.(Leu226Pro). In silico predictions for this variant are consistently pathogenic (Polyphen, SIFT, CADD, Mutation Taster). The variant is absent in population databases (gnomAD, dbSNP, 1000G). The variant has been previously described with uncertain pathogenicity (ClinVar). Analysis of parental samples indicated this variant was paternally inherited. Based on the information available at the time of curation, this variant has been classified as a VARIANT of UNCERTAIN SIGNIFICANCE (VUS). |