Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000479034 | SCV000572972 | pathogenic | not provided | 2017-02-16 | criteria provided, single submitter | clinical testing | The c.3266_3267delCT pathogenic variant in the SETD5 gene causes a frameshift starting with codon Serine 1089, changes this amino acid to a Cysteine residue and creates a premature Stop codon at position 16 of the new reading frame, denoted p.Ser1089CysfsX16. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. The c.3266_3267delCT variant is not observed in large population cohorts (Lek et al., 2016; 1000 Genomes Consortium et al., 2015; Exome Variant Server). Other frameshift and loss of function variants in SETD5 have been reported in association with intellectual disability in the Human Gene Mutation Database (Stenson et al., 2014). |