Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000801528 | SCV000941305 | uncertain significance | Dyskeratosis congenita, autosomal dominant 6 | 2023-12-07 | criteria provided, single submitter | clinical testing | This sequence change replaces serine, which is neutral and polar, with leucine, which is neutral and non-polar, at codon 407 of the ACD protein (p.Ser407Leu). This variant is present in population databases (rs374925782, gnomAD 0.01%). This missense change has been observed in individual(s) with head and neck cancer (PMID: 34598035). ClinVar contains an entry for this variant (Variation ID: 647101). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ACD protein function with a positive predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Institute for Clinical Genetics, |
RCV003238227 | SCV002011183 | uncertain significance | not provided | 2021-11-03 | criteria provided, single submitter | clinical testing | |
Genetic Services Laboratory, |
RCV001816860 | SCV002069252 | uncertain significance | not specified | 2018-09-13 | criteria provided, single submitter | clinical testing | |
Center for Genomic Medicine, |
RCV001816860 | SCV002551709 | uncertain significance | not specified | 2023-08-15 | criteria provided, single submitter | clinical testing | |
Gene |
RCV003238227 | SCV005081092 | uncertain significance | not provided | 2023-12-17 | criteria provided, single submitter | clinical testing | Reported as a germline variant in an individual with early-onset head and neck cancer in the published literature; however, variants in other genes were also identified (PMID: 34598035); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Variants in candidate genes are classified as variants of uncertain significance in accordance with ACMG guidelines (PMID: 25741868); This variant is associated with the following publications: (PMID: 34598035) |