Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV004700053 | SCV005205534 | pathogenic | Leukoencephalopathy-thalamus and brainstem anomalies-high lactate syndrome | 2024-06-24 | criteria provided, single submitter | clinical testing | Variant summary: EARS2 c.428C>G (p.Ser143X) results in a premature termination codon, predicted to cause a truncation of the encoded protein or absence of the protein due to nonsense mediated decay, which are commonly known mechanisms for disease. The variant allele was found at a frequency of 2e-05 in 248880 control chromosomes. To our knowledge, no occurrence of c.428C>G in individuals affected with Leukoencephalopathy-Thalamus And Brainstem Anomalies-High Lactate Syndrome and no experimental evidence demonstrating its impact on protein function have been reported. No submitters have cited clinical-significance assessments for this variant to ClinVar. Based on the evidence outlined above, the variant was classified as pathogenic. |