Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Undiagnosed Diseases Network, |
RCV000558004 | SCV000622147 | uncertain significance | Progressive encephalopathy with leukodystrophy due to DECR deficiency | 2016-03-17 | criteria provided, single submitter | clinical testing | This individual has been reported in PMID:29388319. |
Labcorp Genetics |
RCV000558004 | SCV003264084 | uncertain significance | Progressive encephalopathy with leukodystrophy due to DECR deficiency | 2022-07-07 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Experimental studies and prediction algorithms are not available or were not evaluated, and the functional significance of this variant is currently unknown. ClinVar contains an entry for this variant (Variation ID: 453290). Disruption of the initiator codon has been observed in individual(s) with clinical features of 2,4-dienoyl CoA reductase 1 deficiency (PMID: 29388319). The frequency data for this variant in the population databases is considered unreliable, as metrics indicate poor data quality at this position in the gnomAD database. This sequence change affects the initiator methionine of the NADK2 mRNA. The next in-frame methionine is located at codon 164. |
OMIM | RCV000558004 | SCV001193448 | pathogenic | Progressive encephalopathy with leukodystrophy due to DECR deficiency | 2020-03-31 | no assertion criteria provided | literature only |