Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Mendelics | RCV002247628 | SCV002516072 | uncertain significance | not specified | 2022-05-04 | criteria provided, single submitter | clinical testing | |
Neuberg Centre For Genomic Medicine, |
RCV000203554 | SCV004047819 | uncertain significance | Tremor, hereditary essential, 5 | criteria provided, single submitter | clinical testing | The missense variant c.3412G>A (p.Val1138Met) in TENM4 gene has been reported in heterozygous state in individuals affected with essential tremor (Hor, Hyun et al., 2015). Experimental studies have shown that this missense impact the function of the protein and exert a likely dominant-negative effect (Hor, Hyun et al., 2015). This variant has allele frequency 0.04% in the gnomAD and novel in 1000 genome database. This variant has been reported to the ClinVar database as Pathogenic. The amino acid Val at position 1138 is changed to a Met changing protein sequence and it might alter its composition and physico-chemical properties. The variant is predicted to be damaging by SIFT. The amino acid change p.Val1138Met in TENM4 is predicted as conserved by GERP++ and PhyloP across 100 vertebrates. For these reasons, this variant has been classified as Variant of uncertain significance. | |
OMIM | RCV000203554 | SCV000258617 | pathogenic | Tremor, hereditary essential, 5 | 2015-10-15 | no assertion criteria provided | literature only |