Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics Munich, |
RCV000995476 | SCV001149662 | pathogenic | Actin accumulation myopathy | 2019-06-11 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000995476 | SCV003524161 | uncertain significance | Actin accumulation myopathy | 2022-08-30 | criteria provided, single submitter | clinical testing | This missense change has been observed in individual(s) with clinical features of ACTA1-related conditions (PMID: 19562689). This variant is not present in population databases (gnomAD no frequency). This sequence change replaces aspartic acid, which is acidic and polar, with glutamic acid, which is acidic and polar, at codon 246 of the ACTA1 protein (p.Asp246Glu). This variant is also known as p.Asp244Glu. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ACTA1 protein function. ClinVar contains an entry for this variant (Variation ID: 807360). |
Revvity Omics, |
RCV003141916 | SCV003822531 | uncertain significance | not provided | 2022-12-21 | criteria provided, single submitter | clinical testing | |
Gene |
RCV003141916 | SCV003936715 | likely pathogenic | not provided | 2022-12-30 | criteria provided, single submitter | clinical testing | In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; Not observed at significant frequency in large population cohorts (gnomAD); Missense variants in this gene are often considered pathogenic (HGMD); This variant is associated with the following publications: (PMID: 19562689) |