Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV002472328 | SCV002769695 | uncertain significance | Rett syndrome | 2022-10-11 | reviewed by expert panel | curation | The p.Gln227Glu variant in MECP2 (NM_004992.3) has been reported in an individual with clinical features of MECP2-related conditions (PMID 17383248). The p.Gln227Glu variant in MECP2 is absent from gnomAD (PM2_supporting). The p.Gln227Glu variant is observed in at least 1 unaffected male (internal database - Invitae) (BS2_supporting). In summary, the p.Gln227Glu variant in MECP2 is classified as a Variant of Uncertain Significance based on the ACMG/AMP criteria (PM2_supporting, BS2_supporting). |
Labcorp Genetics |
RCV001522685 | SCV001732272 | benign | Severe neonatal-onset encephalopathy with microcephaly | 2022-08-16 | criteria provided, single submitter | clinical testing | |
Centre for Population Genomics, |
RCV002472328 | SCV004808778 | uncertain significance | Rett syndrome | 2024-03-15 | criteria provided, single submitter | curation | This variant has been collected from RettBASE and curated to current modified ACMG/AMP criteria. Based on the classification scheme defined by the ClinGen Rett/Angelman-like Expert Panel for Rett/AS-like Disorders Specifications to the ACMG/AMP Variant Interpretation Guidelines VCEP 3.0, this variant is classified as a variant of uncertain significance. At least the following criteria are met: This variant is absent from gnomAD (PM2_Supporting). |
Rett |
RCV000133197 | SCV000188195 | uncertain significance | X-linked intellectual disability-psychosis-macroorchidism syndrome | 2007-11-01 | no assertion criteria provided | curation |