Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Neuromuscular Department, |
RCV001002747 | SCV001156521 | uncertain significance | Charcot-Marie-Tooth disease, type I | 2019-02-20 | criteria provided, single submitter | clinical testing | |
Gene |
RCV001585911 | SCV001819851 | likely benign | not provided | 2020-12-29 | criteria provided, single submitter | clinical testing | This variant is associated with the following publications: (PMID: 32122354) |
Labcorp Genetics |
RCV001585911 | SCV002510796 | uncertain significance | not provided | 2024-10-15 | criteria provided, single submitter | clinical testing | This sequence change replaces valine, which is neutral and non-polar, with alanine, which is neutral and non-polar, at codon 469 of the SEPT9 protein (p.Val469Ala). This variant is present in population databases (rs376712636, gnomAD 0.02%). This missense change has been observed in individual(s) with clinical features of Charcot-Marie-Tooth disease (PMID: 32122354). ClinVar contains an entry for this variant (Variation ID: 812141). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) indicates that this missense variant is not expected to disrupt SEPT9 protein function with a negative predictive value of 80%. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Clinical Genetics, |
RCV001585911 | SCV001924339 | uncertain significance | not provided | no assertion criteria provided | clinical testing | ||
Joint Genome Diagnostic Labs from Nijmegen and Maastricht, |
RCV001585911 | SCV001952137 | uncertain significance | not provided | no assertion criteria provided | clinical testing |