Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001756536 | SCV001985414 | uncertain significance | not provided | 2021-04-26 | criteria provided, single submitter | clinical testing | Observed in a patient with Gitelman syndrome in published literature (Fava et al., 2007); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 17654016) |
Labcorp Genetics |
RCV001756536 | SCV002307547 | likely pathogenic | not provided | 2024-05-14 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with serine, which is neutral and polar, at codon 876 of the SLC12A3 protein (p.Gly876Ser). This variant is present in population databases (rs370301695, gnomAD 0.01%). This missense change has been observed in individuals with Gitelman syndrome (PMID: 17654016; Invitae). ClinVar contains an entry for this variant (Variation ID: 1303037). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt SLC12A3 protein function with a positive predictive value of 80%. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
European Hospital Georges Pompidou Genetics Department, |
RCV002243457 | SCV002513822 | likely pathogenic | Familial hypokalemia-hypomagnesemia | 2022-04-27 | criteria provided, single submitter | clinical testing | ACMG criteria used:PM1 PM2 PM3 PP5 |