Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
HUSP Clinical Genetics Laboratory, |
RCV001328004 | SCV001519335 | likely pathogenic | Developmental and epileptic encephalopathy, 5 | 2021-01-14 | no assertion criteria provided | clinical testing | The variant was detected in a 4-year-old boy with generalized tonic-clonic epilepsy. The c.4640T>A variant in the SPTAN1 gene (NM_001130438.3) consists of an amino acid change (p.Leu1547Gln). This alteration has not been reported previously in the literature and it is not detected in the general population. The in-silico tools predict that it is very likely to affect the protein function. Pathological variants in the SPTAN1 gene are associated with the phenotype of Developmental and epileptic encephalopathy 5 (OMIM: 613477) with autosomal dominant inheritance. The genetic study of the parents was carried out using the Sanger sequencing method and they did not present the alteration, so it is a de novo variant in the child. Therefore, the clinical significance of the c.4640T>A variant is likely pathogenic. |