Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV001782995 | SCV002026427 | likely pathogenic | Landau-Kleffner syndrome | 2019-01-01 | criteria provided, single submitter | research | |
Labcorp Genetics |
RCV001782995 | SCV002120347 | likely pathogenic | Landau-Kleffner syndrome | 2022-03-29 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 433130). This missense change has been observed in individual(s) with clinical features of GRIN2A-related conditions (PMID: 23933819, 29358611). It has also been observed to segregate with disease in related individuals. This variant is present in population databases (no rsID available, gnomAD 0.0009%). This sequence change replaces proline, which is neutral and non-polar, with arginine, which is basic and polar, at codon 79 of the GRIN2A protein (p.Pro79Arg). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt GRIN2A protein function. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Experimental studies have shown that this missense change affects GRIN2A function (PMID: 27288002, 28242877). |
Bioinformatics Core, |
RCV000656053 | SCV000588329 | pathogenic | Childhood epilepsy with centrotemporal spikes | 2017-01-01 | no assertion criteria provided | case-control | CAADphred>15 |