Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000703113 | SCV000831995 | likely pathogenic | Early infantile epileptic encephalopathy with suppression bursts | 2018-05-25 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive, but these predictions have not been confirmed by published functional studies and their clinical significance is uncertain. This variant has been observed to be de novo in individuals affected with clinical features consistent with an SCN1A-related disease (Invitae). This variant is not present in population databases (ExAC no frequency). This sequence change replaces leucine with proline at codon 186 of the SCN1A protein (p.Leu186Pro). The leucine residue is highly conserved and there is a moderate physicochemical difference between leucine and proline. |
Juno Genomics, |
RCV004796286 | SCV005418048 | uncertain significance | Migraine, familial hemiplegic, 3; Severe myoclonic epilepsy in infancy; Generalized epilepsy with febrile seizures plus, type 2; Developmental and epileptic encephalopathy 6B | criteria provided, single submitter | clinical testing | PM2_Supporting+PP3+PS2_Supporting+PP2 |